Hormone Therapy

Personalized parathyroid hormone therapy for hypoparathyroidism: Insights from pharmacokinetic-pharmacodynamic modelling.

TL;DR

Continuous administration of PTH is favoured over intermittent dosing because it permanently increases phosphate clearance, as demonstrated through a PKPD model developed from a single patient treated with multiple PTH dosing regimens including continuous infusion.

Key Findings

A one-compartment PKPD model for PTH was developed using Edsim++ that described the effect of PTH through relative clearance of calcium and phosphate.

  • The model was constructed from data of a single 42-year-old male patient with chronic primary hypoparathyroidism following total thyroidectomy
  • PTH was measured in plasma; calcium and phosphate were measured in both plasma and urine
  • The patient received intermittent PTH followed by off-label continuous infusion of PTH
  • Various dosing regimens were studied, including continuous infusion

The PKPD model showed a marked effect of PTH on phosphate clearance but less effect on calcium clearance.

  • The PKPD model 'showed visually a marked effect on phosphate clearance, but less on calcium clearance'
  • Phosphate was chosen as the primary effect parameter because the patient received concomitant medications that influenced calcium homeostasis but to a lesser extent phosphate homeostasis
  • This made phosphate a more reliable pharmacodynamic endpoint than calcium for model development

The EC50 for PTH effect on phosphate clearance was determined to be 6.3 pmol/L PTH.

  • EC50 of 6.3 pmol/L PTH was derived using phosphate as the effect parameter
  • This value was obtained from the completed PKPD model using data from the single patient
  • The EC50 represents the PTH plasma concentration at which half-maximal effect on phosphate clearance is achieved

Once-daily administration of PTH per dosing guidelines adequately controls calcium plasma levels but has only a transient effect on urinary calcium excretion, which does not lower the risk of nephrolithiasis.

  • The patient developed recurrent nephrolithiasis on conventional therapy, prompting consideration of rhPTH(1-84) treatment
  • According to the dosing guideline for PTH, calcium plasma levels are adequately controlled with once-daily administration
  • However, 'the effect on urinary calcium excretion is only transient and hence does not lower the risk of nephrolithiasis'
  • This limitation of once-daily dosing motivated the investigation of multiple-daily or continuous administration

Continuous administration of PTH is favoured over intermittent dosing because it permanently increases phosphate clearance.

  • Continuous administration 'permanently increases the phosphate clearance' compared to intermittent dosing regimens
  • The PKPD model was completed with data from a single patient who received PTH according to various dosing regimens including continuous infusion
  • Continuous PTH administration was given as an off-label infusion
  • The authors concluded that continuous administration of PTH 'needs to be further investigated'

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Citation

Visscher M, Schuls-Fouchier M, Berends A, Muller Kobold A, Punt N, Touw D. (2025). Personalized parathyroid hormone therapy for hypoparathyroidism: Insights from pharmacokinetic-pharmacodynamic modelling.. British journal of clinical pharmacology. https://doi.org/10.1111/bcp.16342